Small heat-shock protein HSPB3 promotes myogenesis by regulating the lamin B receptor

Research output: Contribution to journalResearch articleContributedpeer-review

Contributors

  • Tatiana Tiago - , University of Modena and Reggio Emilia (Author)
  • Barbara Hummel - , Max Planck Institute of Immunobiology and Epigenetics (Author)
  • Federica F. Morelli - , University of Modena and Reggio Emilia (Author)
  • Valentina Basile - , University of Modena and Reggio Emilia (Author)
  • Jonathan Vinet - , University of Modena and Reggio Emilia (Author)
  • Veronica Galli - , University of Modena and Reggio Emilia (Author)
  • Laura Mediani - , University of Modena and Reggio Emilia (Author)
  • Francesco Antoniani - , University of Modena and Reggio Emilia (Author)
  • Silvia Pomella - , IRCCS Ospedale pediatrico Bambino Gesù - Roma (Author)
  • Matteo Cassandri - , IRCCS Ospedale pediatrico Bambino Gesù - Roma (Author)
  • Maria Giovanna Garone - , University of Rome La Sapienza (Author)
  • Beatrice Silvestri - , University of Rome La Sapienza, Italian Institute of Technology (Author)
  • Marco Cimino - , University of Modena and Reggio Emilia (Author)
  • Giovanna Cenacchi - , University of Bologna (Author)
  • Roberta Costa - , University of Bologna (Author)
  • Vincent Mouly - , Sorbonne Université (Author)
  • Ina Poser - , Max Planck Institute of Molecular Cell Biology and Genetics, Dewpoint Therapeutics GmbH (Author)
  • Esti Yeger-Lotem - , Ben-Gurion University of the Negev (Author)
  • Alessandro Rosa - , University of Rome La Sapienza, Italian Institute of Technology (Author)
  • Simon Alberti - , Biotechnology Center, Chair of Cellular Biochemistry (Author)
  • Rossella Rota - , IRCCS Ospedale pediatrico Bambino Gesù - Roma (Author)
  • Anat Ben-Zvi - , Ben-Gurion University of the Negev (Author)
  • Ritwick Sawarkar - , Max Planck Institute of Immunobiology and Epigenetics, University of Cambridge (Author)
  • Serena Carra - , University of Modena and Reggio Emilia (Author)

Abstract

One of the critical events that regulates muscle cell differentiation is the replacement of the lamin B receptor (LBR)-tether with the lamin A/C (LMNA)-tether to remodel transcription and induce differentiation-specific genes. Here, we report that localization and activity of the LBR-tether are crucially dependent on the muscle-specific chaperone HSPB3 and that depletion of HSPB3 prevents muscle cell differentiation. We further show that HSPB3 binds to LBR in the nucleoplasm and maintains it in a dynamic state, thus promoting the transcription of myogenic genes, including the genes to remodel the extracellular matrix. Remarkably, HSPB3 overexpression alone is sufficient to induce the differentiation of two human muscle cell lines, LHCNM2 cells, and rhabdomyosarcoma cells. We also show that mutant R116P-HSPB3 from a myopathy patient with chromatin alterations and muscle fiber disorganization, forms nuclear aggregates that immobilize LBR. We find that R116P-HSPB3 is unable to induce myoblast differentiation and instead activates the unfolded protein response. We propose that HSPB3 is a specialized chaperone engaged in muscle cell differentiation and that dysfunctional HSPB3 causes neuromuscular disease by deregulating LBR.

Details

Original languageEnglish
Article number452
JournalCell death and disease
Volume12
Issue number5
Publication statusPublished - May 2021
Peer-reviewedYes

External IDs

PubMed 33958580
ORCID /0000-0003-4017-6505/work/142253851