Atp6ap2 deletion causes extensive vacuolation that consumes the insulin content of pancreatic β cells

Publikation: Beitrag in FachzeitschriftForschungsartikelBeigetragenBegutachtung

Beitragende

  • Katrina J Binger - , La Trobe University (Autor:in)
  • Martin Neukam - , Molekulare Diabetologie, Technische Universität Dresden, Universitätsklinikum Carl Gustav Carus Dresden (Autor:in)
  • Sudhir Gopal Tattikota - , Massachusetts General Hospital (Autor:in)
  • Fatimunnisa Qadri - , Max-Delbrück-Centrum für Molekulare Medizin (MDC) (Autor:in)
  • Dmytro Puchkov - , Leibniz-Forschungsinstitut für Molekulare Pharmakologie (Autor:in)
  • Diana M Willmes - , Universitätsklinikum Carl Gustav Carus Dresden (Autor:in)
  • Sabrina Wurmsee - , Max-Delbrück-Centrum für Molekulare Medizin (MDC) (Autor:in)
  • Sabrina Geisberger - , Max-Delbrück-Centrum für Molekulare Medizin (MDC) (Autor:in)
  • Ralf Dechend - , Experimental and Clinical Research Center (ECRC) (Autor:in)
  • Klemens Raile - , Experimental and Clinical Research Center (ECRC) (Autor:in)
  • Thomas Kurth - , Core Facility Elektronenmikroskopie & Histologie, Center for Molecular and Cellular Bioengineering (CMCB), Center for Regenerative Therapies Dresden (CRTD) (Autor:in)
  • Genevieve Nguyen - , Center for Interdisciplinary Research in Biology (Autor:in)
  • Matthew N Poy - , Max-Delbrück-Centrum für Molekulare Medizin (MDC) (Autor:in)
  • Michele Solimena - , Molekulare Diabetologie, Technische Universität Dresden, Universitätsklinikum Carl Gustav Carus Dresden (Autor:in)
  • Dominik N Muller - , Max-Delbrück-Centrum für Molekulare Medizin (MDC) (Autor:in)
  • Andreas L Birkenfeld - , Molekulare Diabetologie, Technische Universität Dresden, Universitätsklinikum Carl Gustav Carus Dresden, Universitätsklinikum Tübingen, Helmholtz Zentrum München - Deutsches Forschungszentrum für Gesundheit und Umwelt, Eberhard Karls Universität Tübingen, King's College London (KCL) (Autor:in)

Abstract

Pancreatic β cells store insulin within secretory granules which undergo exocytosis upon elevation of blood glucose levels. Crinophagy and autophagy are instead responsible to deliver damaged or old granules to acidic lysosomes for intracellular degradation. However, excessive consumption of insulin granules can impair β cell function and cause diabetes. Atp6ap2 is an essential accessory component of the vacuolar ATPase required for lysosomal degradative functions and autophagy. Here, we show that Cre recombinase-mediated conditional deletion of Atp6ap2 in mouse β cells causes a dramatic accumulation of large, multigranular vacuoles in the cytoplasm, with reduction of insulin content and compromised glucose homeostasis. Loss of insulin stores and gigantic vacuoles were also observed in cultured insulinoma INS-1 cells upon CRISPR/Cas9-mediated removal of Atp6ap2. Remarkably, these phenotypic alterations could not be attributed to a deficiency in autophagy or acidification of lysosomes. Together, these data indicate that Atp6ap2 is critical for regulating the stored insulin pool and that a balanced regulation of granule turnover is key to maintaining β cell function and diabetes prevention.

Details

OriginalspracheEnglisch
Seiten (von - bis)19983-19988
Seitenumfang6
FachzeitschriftProceedings of the National Academy of Sciences of the United States of America : PNAS
Jahrgang116
Ausgabenummer40
PublikationsstatusVeröffentlicht - 1 Okt. 2019
Peer-Review-StatusJa

Externe IDs

PubMedCentral PMC6778207
Scopus 85072758913
ORCID /0000-0001-5624-1717/work/142239057

Schlagworte

Ziele für nachhaltige Entwicklung

Schlagwörter

  • Animals, Autophagy, CRISPR-Cas Systems, Cytosol/metabolism, Female, Gene Deletion, Gene Silencing, Insulin/metabolism, Insulin-Secreting Cells/metabolism, Insulinoma/metabolism, Lysosomes/metabolism, Male, Mice, Phenotype, Promoter Regions, Genetic, Proton-Translocating ATPases/genetics, RNA, Small Interfering/metabolism, Rats, Receptors, Cell Surface/genetics, Receptors, Estrogen/metabolism, Vacuolar Proton-Translocating ATPases/metabolism, Vacuoles/metabolism